Hirschsprung disease

References

Key articles

Montalva L, Cheng LS, Kapur R, et al. Hirschsprung disease. Nat Rev Dis Primers. 2023 Oct 12;9(1):54. Abstract

Kawaguchi AL, Guner YS, Sømme S, et al. Management and outcomes for long-segment Hirschsprung disease: a systematic review from the APSA outcomes and evidence based practice committee. J Pediatr Surg. 2021 Sep;56(9):1513-23.Full text  Abstract

Gosain A, Frykman PK, Cowles RA, et al. Guidelines for the diagnosis and management of Hirschsprung-associated enterocolitis. Pediatr Surg Int. 2017 May 33(5):517-21.Full text  Abstract

Kyrklund K, Sloots CEJ, de Blaauw I, et al. ERNICA guidelines for the management of rectosigmoid Hirschsprung's disease. Orphanet J Rare Dis. 2020 Jun 25;15(1):164.Full text  Abstract

Granström AL, Irvine W, Hoel AT, et al. Ernica clinical consensus statements on total colonic and intestinal aganglionosis. J Pediatr Surg. 2024 Oct;59(10):161565.Full text  Abstract

Reference articles

1. Montalva L, Cheng LS, Kapur R, et al. Hirschsprung disease. Nat Rev Dis Primers. 2023 Oct 12;9(1):54. Abstract

2. Peña A, Bischoff A. Hirchsprung disease. In: Peña A, Bischoff A, eds. Surgical treatment of colorectal problems in children. Cham, Switzerland: Springer International Publishing; 2015:399-436.

3. Pastor AC, Osman F, Teitelbaum DH, et al. Development of a standardized definition for Hirschsprung's-associated enterocolitis: a Delphi analysis. J Pediatr Surg. 2009 Jan;44(1):251-6. Abstract

4. Kawaguchi AL, Guner YS, Sømme S, et al. Management and outcomes for long-segment Hirschsprung disease: a systematic review from the APSA outcomes and evidence based practice committee. J Pediatr Surg. 2021 Sep;56(9):1513-23.Full text  Abstract

5. Butler Tjaden NE, Trainor PA. The developmental etiology and pathogenesis of Hirschsprung disease. Transl Res. 2013 Jul;162(1):1-15.Full text  Abstract

6. Langer JC. Hirschsprung disease. Curr Opin Pediatr. 2013 Jun;25(3):368-74. Abstract

7. Huerta CT, Ramsey WA, Davis JK, et al. Nationwide outcomes of newborns with rectosigmoid versus long-segment Hirschsprung disease. J Pediatr Surg. 2023 May;58(5):849-55. Abstract

8. Moore SW. Total colonic aganglionosis in Hirschsprung disease. Semin Pediatr Surg. 2012 Nov;21(4):302-9. Abstract

9. Cordeiro-Rudnisky F, Ahn S, Sheuka N, et al. Transition zone in total colonic aganglionosis and colorectal Hirschsprung's disease shows a similar trend of mucosal innervation: image processing and analysis study. Pediatr Dev Pathol. 2020 Mar-Apr;23(2):127-31. Abstract

10. Ruttenstock E, Puri P. A meta-analysis of clinical outcome in patients with total intestinal aganglionosis. Pediatr Surg Int. 2009;25:833-9. Abstract

11. Gosain A, Frykman PK, Cowles RA, et al. Guidelines for the diagnosis and management of Hirschsprung-associated enterocolitis. Pediatr Surg Int. 2017 May 33(5):517-21.Full text  Abstract

12. Lewit RA, Kuruvilla KP, Fu M, et al. Current understanding of Hirschsprung-associated enterocolitis: pathogenesis, diagnosis and treatment. Semin Pediatr Surg. 2022 Apr;31(2):151162.Full text  Abstract

13. Knaus ME, Pendola G, Srinivas S, et al. Social determinants of health and Hirschsprung-associated enterocolitis. J Pediatr Surg. 2023 Aug;58(8):1458-62. Abstract

14. Arliss J, Holgersen LO. Neonatal appendiceal perforation and Hirschsprung's disease. J Pediatr Surg. 1990 Jun;25(6):694-5. Abstract

15. Beltman L, Labib H, Oosterlaan J, et al. Risk factors for complications in patients with Hirschsprung disease while awaiting surgery: beware of bowel perforation. J Pediatr Surg. 2022 Nov;57(11):561-8.Full text  Abstract

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17. Anderson JE, Vanover MA, Saadai P, et al. Epidemiology of Hirschsprung disease in California from 1995 to 2013. Pediatr Surg Int. 2018 Dec;34(12):1299-1303.Full text  Abstract

18. Passarge E. The genetics of Hirschsprung's disease. Evidence for heterogeneous etiology and a study of sixty-three families. N Engl J Med. 1967;276:138-43. Abstract

19. Karim A, Tang CS, Tam PK. The emerging genetic landscape of Hirschsprung disease and its potential clinical applications. Front Pediatr. 2021;9:638093.Full text  Abstract

20. Xiao J, Hao LW, Wang J, et al. Comprehensive characterization of the genetic landscape of familial Hirschsprung's disease. World J Pediatr. 2023 Jul;19(7):644-51.Full text  Abstract

21. Moore SW. The contribution of associated congenital anomalies in understanding Hirschsprung's disease. Pediatr Surg Int. 2006;22:305-15. Abstract

22. Friedmacher F, Puri P. Hirschsprung's disease associated with Down syndrome: a meta-analysis of incidence, functional outcomes and mortality. Pediatr Surg Int. 2013 Sep;29(9):937-46. Abstract

23. Moore SW. Chromosomal and related Mendelian syndromes associated with Hirschsprung's disease. Pediatr Surg Int. 2012 Nov;28(11):1045-58. Abstract

24. Amiel J, Sproat-Emison E, Garcia-Barcelo M, et al. Hirschsprung disease, associated syndromes and genetics: a review. J Med Genet. 2008 Jan;45(1):1-14.Full text  Abstract

25. Hofmann AD, Puri P. Association of Hirschsprung's disease and anorectal malformation: a systematic review. Pediatr Surg Int. 2013 Sep;29(9):913-7.Full text  Abstract

26. Tilghman JM, Ling AY, Turner TN, et al. Molecular genetic anatomy and risk profile of Hirschsprung's disease. N Engl J Med. 2019 Apr 11;380(15):1421-32.Full text  Abstract

27. Kyrklund K, Sloots CEJ, de Blaauw I, et al. ERNICA guidelines for the management of rectosigmoid Hirschsprung's disease. Orphanet J Rare Dis. 2020 Jun 25;15(1):164.Full text  Abstract

28. Emison ES, McCallion AS, Kashuk CS, et al. A common sex-dependent mutation in a RET enhancer underlies Hirschsprung disease risk. Nature. 2005 Apr 14;434(7035):857-63. Abstract

29. Best KE, Addor MC, Arriola L, et al. Hirschsprung's disease prevalence in Europe: a register based study. Birth Defects Res A Clin Mol Teratol. 2014 Sep;100(9):695-702. Abstract

30. Edery P, Attié T, Amiel J, et al. Mutation of the endothelin-3 gene in the Waardenburg-Hirschsprung disease (Shah-Waardenburg syndrome). Nat Genet. 1996 Apr;12(4):442-4. Abstract

31. Woo HY, Oh C, Han JW, et al. Clinical features of children with Haddad syndrome: a single-center experience. J Pediatr Surg. 2020 Mar;55(3):387-92. Abstract

32. Elema JD, de Vries JA, Vos LJ. Intensity and proximal extension of acetylcholinesterase activity in the mucosa of the rectosigmoid in Hirschsprung's disease. J Pediatr Surg. 1973;8:361-8. Abstract

33. Howard ER. Hirschsprung's disease: a review of the morphology and physiology. Postgrad Med J. 1972;48:471-7. Abstract

34. Howard ER. Histochemistry in the diagnosis and investigation of congenital aganglionosis (Hirschsprung's disease). Am Surg. 1973;39:602-7. Abstract

35. Lawal TA, Chatoorgoon K, Collins MH, et al. Redo pull-through in Hirschsprung's [corrected] disease for obstructive symptoms due to residual aganglionosis and transition zone bowel. J Pediatr Surg. 2011;46:342-7. Abstract

36. Okamoto E, Ueda T. Embryogenesis of intramural ganglia of the gut and its relation to Hirschsprung's disease. J Pediatr Surg. 1967;2:437.

37. Barlow A, de Graaff E, Pachnis V. Enteric nervous system progenitors are coordinately controlled by the G protein-coupled receptor EDNRB and the receptor tyrosine kinase RET. Neuron. 2003 Dec 4;40(5):905-16.Full text  Abstract

38. Hiatt RB. A further description of the pathologic physiology of congenital megacolon and the results of surgical treatment. Pediatrics. 1958;21:825-31. Abstract

39. Tobon F, Reid NC, Talbert JL, et al. Nonsurgical test for the diagnosis of Hirschsprung's disease. N Engl J Med. 1968;278:188-93. Abstract

40. O'Kelly TJ, Davies JR, Tam PK, et al. Abnormalities of nitric-oxide producing neurons in Hirschsprung's disease: morphology and implications. J Pediatr Surg. 1994;29:294-9. Abstract

41. Bealer JF, Natuzzi ES, Buscher C, et al. Nitric oxide synthase is deficient in the aganglionic colon of patients with Hirschsprung's disease. Pediatrics. 1994;93:647-51. Abstract

42. Pini Prato A, Arnoldi R, Sgrò A, et al. Hirschsprung disease and Down syndrome: from the reappraisal of risk factors to the impact of surgery. J Pediatr Surg. 2019 Sep;54(9):1838-42. Abstract

43. Saberi RA, Gilna GP, Slavin BV, et al. Hirschsprung disease in Down syndrome: an opportunity for improvement. J Pediatr Surg. 2022 Jun;57(6):1040-4. Abstract

44. Mc Laughlin D, Puri P. Familial Hirschsprung's disease: a systematic review. Pediatr Surg Int. 2015 Aug;31(8):695-700. Abstract

45. Coyle D, Puri P. Hirschsprung's disease in children with Mowat-Wilson syndrome. Pediatr Surg Int. 2015 Aug;31(8):711-7. Abstract

46. Wehrli LA, Reppucci ML, Ketzer J, et al. Incidence of medullary thyroid carcinoma and Hirschsprung disease based on the cosmos database. Pediatr Surg Int. 2023 Jul 7;39(1):227. Abstract

47. Ostertag-Hill CA, Nandivada P, Dickie BH. Late diagnosis of Hirschsprung disease: clinical presentation and long-term functional outcomes. J Pediatr Surg. 2024 Feb;59(2):220-4. Abstract

48. Diamond IR, Casadiego G, Traubici J, et al. The contrast enema for Hirschsprung disease: predictors of a false-positive result. J Pediatr Surg. 2007 May;42(5):792-5. Abstract

49. Chen X, Xiaojuan W, Zhang H, et al. Diagnostic value of the preoperatively detected radiological transition zone in Hirschsprung's disease. Pediatr Surg Int. 2017 May;33(5):581-6. Abstract

50. Proctor ML, Traubici J, Langer JC, et al. Correlation between radiographic transition zone and level of aganglionosis in Hirschsprung's disease: implications for surgical approach. J Pediatr Surg. 2003 May;38(5):775-8. Abstract

51. Green N, Smith CA, Bradford MC, et al. Rectal suction biopsy versus incisional rectal biopsy in the diagnosis of Hirschsprung disease. Pediatr Surg Int. 2022 Dec;38(12):1989-96. Abstract

52. Friedmacher F, Puri P. Rectal suction biopsy for the diagnosis of Hirschsprung's disease: a systematic review of diagnostic accuracy and complications. Pediatr Surg Int. 2015 Sep;31(9):821-30. Abstract

53. Hwang S, Kapur RP. Advances and pitfalls in the diagnosis of Hirschsprung disease. Surg Pathol Clin. 2020 Dec;13(4):567-79. Abstract

54. Ambartsumyan L, Smith C, Kapur RP. Diagnosis of Hirschsprung disease. Pediatr Dev Pathol. 2020 Jan-Feb;23(1):8-22. Abstract

55. Meinds RJ, Trzpis M, Broens PMA. Anorectal manometry may reduce the number of rectal suction biopsy procedures needed to diagnose Hirschsprung disease. J Pediatr Gastroenterol Nutr. 2018 Sep;67(3):322-7.Full text  Abstract

56. Frykman PK, Kim S, Wester T, et al. Critical evaluation of the Hirschsprung-associated enterocolitis (HAEC) score: a multicenter study of 116 children with Hirschsprung disease. J Pediatr Surg. 2018 Apr;53(4):708-17.Full text  Abstract

57. Zhu T, Zhang G, Meng X, et al. Enterocolitis is a risk factor for bowel perforation in neonates with Hirschsprung's disease: a retrospective multicenter study. Front Pediatr. 2022 Feb 7;10:807607.Full text  Abstract

58. Buonpane C, Lautz TB, Hu YY. Should we look for Hirschsprung disease in all children with meconium plug syndrome? J Pediatr Surg. 2019 Jun;54(6):1164-7. Abstract

59. Granström AL, Irvine W, Hoel AT, et al. Ernica clinical consensus statements on total colonic and intestinal aganglionosis. J Pediatr Surg. 2024 Oct;59(10):161565.Full text  Abstract

60. Journal of Laparoendoscopic & Advanced Surgical Techniques. March 2005, 15(1): 89-91.Full text  Abstract

61. Georgeson KE, Fuenfer MM, Hardin WD. Primary laparoscopic pull-through for Hirschsprung's disease in infants and children. J Pediatr Surg. 1995;30:1017-21. Abstract

62. Smith BM, Steiner RB, Lobe TE. Laparoscopic Duhamel pullthrough procedure for Hirschsprung's disease in childhood. J Laparoendosc Surg. 1994;4:273-6. Abstract

63. Kim AC, Langer JC, Pastor AC, et al. Endorectal pull-through for Hirschsprung's disease - a multicenter, long-term comparison of results: transanal vs transabdominal approach. J Pediatr Surg. 2010;45:1213-20. Abstract

64. Badner JA, Sieber WK, Garver KL, et al. A genetic study of Hirschsprung disease. Am J Hum Genet. 1990;46:568-80.Full text  Abstract

65. Carcassonne M, Morisson-Lacombe G, Letourneau JN. Primary corrective operation without decompression in infants less than three months of age with Hirschsprung's disease. J Pediatr Surg. 1982;17:241-3. Abstract

66. So HB, Schwartz DL, Becker JM, et al. Endorectal "pull-through" without preliminary colostomy in neonates with Hirschsprung's disease. J Pediatr Surg. 1980;15:470-1. Abstract

67. Zani A, Eaton S, Morini F, et al. European Paediatric Surgeons' Association survey on the management of Hirschsprung disease. Eur J Pediatr Surg. 2017 Feb;27(1):96-101. Abstract

68. Freedman-Weiss MR, Chiu AS, Caty MG, et al. Delay in operation for Hirschsprung disease is associated with decreased length of stay: a 5-Year NSQIP-Peds analysis. J Perinatol. 2019 Aug;39(8):1105-10. Abstract

69. Soave F. Hirschsprung's disease - a new surgical technique. Arch Dis Child. 1964;39:116-24. Abstract

70. Duhamel B. Retrorectal and transanal pull-through procedure for the treatment of Hirschsprung's disease. Dis Colon Rectum. 1964;7:455-8. Abstract

71. Chatoorgoon K, Pena A, Lawal TA, et al. The problematic Duhamel pouch in Hirschsprung's disease: manifestations and treatment. Eur J Pediatr Surg. 2011;21:366-9. Abstract

72. Lynn HB, van Heerden JA. Rectal myectomy in Hirschsprung's disease: a decade of experience. Arch Surg. 1975;110:991-4. Abstract

73. Levitt MA, Hamrick MC, Eradi B, et al. Transanal, full-thickness, Swenson-like approach for Hirschsprung disease. J Pediatr Surg. 2013;48:2289-95. Abstract

74. Swenson O, Bill AH Jr. Resection of rectum and rectosigmoid with preservation of the sphincter for benign spastic lesions producing megacolon; an experimental study. Surgery. 1948 Aug;24(2):212-20.

75. El-Sawaf MI, Drongowski RA, Chamberlain JN, et al. Are the long-term results of the transanal pull-through equal to those of the transabdominal pull-through? A comparison of the two approaches for Hirschsprung's disease. J Pediatr Surg. 2007;42:41-7. Abstract

76. Langer JC, Durrant AC, de la Torre L, et al. One-stage transanal Soave pullthrough for Hirschsprung's disease: a multi-center experience with 141 children. Ann Surg. 2003;238:569-76.Full text  Abstract

77. Yancey AG, Cromartie JE Jr, Ford JR, et al. A modification of the Swenson technique for congenital megacolon. J Natl Med Assoc. 1952 Sep;44(5):356-63.Full text

78. Woode D, Avansino J, Sawin R, et al. Asa G Yancey: the first to describe a modification of the Swenson technique for Hirschsprung disease. J Pediatr Surg. 2022 Aug;57(8):1701-3. Abstract

79. Chen Y, Nah SA, Laksmi NK, et al. Transanal endorectal pull-through versus transabdominal approach for Hirschsprung's disease: a systematic review and meta-analysis. J Pediatr Surg. 2013;48:642-51. Abstract

80. Duhamel B. A new operation for the treatment of Hirschsprung's disease. Arch Dis Child. 1960 Feb;35(179):38-9.Full text

81. Veras LV, Arnold M, Avansino JR, et al. Guidelines for synoptic reporting of surgery and pathology in Hirschsprung disease. J Pediatr Surg. 2019 Oct;54(10):2017-23.Full text  Abstract

82. Stenström P, Kyrklund K, Bräutigam M, et al. Total colonic aganglionosis: multicentre study of surgical treatment and patient-reported outcomes up to adulthood. BJS Open. 2020 Oct;4(5):943-53.Full text  Abstract

83. Swenson O, Bill AH. Resection of rectum and rectosigmoid with preservation of the sphincter for benign spastic lesions producing megacolon: an experimental study. Surgery. 1948;24:212.

84. Sandgren K, Ekblad E, Larsson LT. Survival of neurons and interstitial cells of Cajal after autotransplantation of myenteric ganglia from small intestine in the lethal spotted mouse. Pediatr Surg Int. 2000;16:272-6. Abstract

85. Hu H, Ding Y, Mu W, et al. DRG-derived neural progenitors differentiate into functional enteric neurons following transplantation in the postnatal colon. Cell Transplant. 2019 Feb;28(2):157-69.Full text  Abstract

86. Lai FP, Lau ST, Wong JK, et al. Correction of Hirschsprung-associated mutations in human induced pluripotent stem cells via clustered regularly interspaced short palindromic repeats/Cas9, restores neural crest cell function. Gastroenterology. 2017 Jul;153(1):139-53.Full text  Abstract

87. Rodríguez-Rodríguez DR, Ramírez-Solís R, Garza-Elizondo MA, et al. Genome editing: A perspective on the application of CRISPR/Cas9 to study human diseases (Review). Int J Mol Med. 2019 Apr;43(4):1559-74.Full text  Abstract

88. Ambartsumyan L, Patel D, Kapavarapu P, et al. Evaluation and management of postsurgical patient with Hirschsprung disease neurogastroenterology & motility committee: position paper of North American Society of Pediatric Gastroenterology, Hepatology, and Nutrition (NASPGHAN). J Pediatr Gastroenterol Nutr. 2023 Apr 1;76(4):533-46.Full text  Abstract

89. Langer JC, Rollins MD, Levitt M, et al. Guidelines for the management of postoperative obstructive symptoms in children with Hirschsprung disease. Pediatr Surg Int. 2017 May;33(5):523-6. Abstract

90. Saadai P, Trappey AF, Goldstein AM, et al. Guidelines for the management of postoperative soiling in children with Hirschsprung disease. Pediatr Surg Int. 2019 Aug;35(8):829-34. Abstract

91. Gunadi, Karina SM, Dwihantoro A. Outcomes in patients with Hirschsprung disease following definitive surgery. BMC Res Notes. 2018 Sep 4;11(1):644.Full text  Abstract

92. Stensrud KJ, Emblem R, Bjørnland K. Late diagnosis of Hirschsprung disease--patient characteristics and results. J Pediatr Surg. 2012 Oct;47(10):1874-9. Abstract

93. Pini Prato A, Erculiani M, Novi ML, et al. Delayed diagnosis in Hirschsprung disease. Pediatr Surg Int. 2024 Mar 4;40(1):65. Abstract

94. Allin BSR, Opondo C, Bradnock TJ, et al. Outcomes at five to eight years of age for children with Hirschsprung's disease. Arch Dis Child. 2021 Apr 21;106(5):484-90.Full text  Abstract

95. Dai Y, Deng Y, Lin Y, et al. Long-term outcomes and quality of life of patients with Hirschsprung disease: a systematic review and meta-analysis. BMC Gastroenterol. 2020 Mar 12;20(1):67.Full text  Abstract

96. Svetanoff WJ, Kapalu CL, Lopez JJ, et al. Psychosocial factors affecting quality of life in patients with anorectal malformation and Hirschsprung disease-a qualitative systematic review. J Pediatr Surg. 2022 Mar;57(3):387-93. Abstract

97. Meinds RJ, van der Steeg AFW, Sloots CEJ, et al. Long-term functional outcomes and quality of life in patients with Hirschsprung's disease. Br J Surg. 2019 Mar;106(4):499-507.Full text  Abstract

98. Harrington AW, Gasior AC, Einarsdottir H, et al. Hirschsprung disease: the rise of structured transition and long-term care. J Pediatr Gastroenterol Nutr. 2019 Sep;69(3):306-9. Abstract

99. Westfal ML, Okiemy O, Chung PHY, et al. Optimal timing for soave primary pull-through in short-segment Hirschsprung disease: a meta-analysis. J Pediatr Surg. 2022 Apr;57(4):719-25.Full text  Abstract

100. Wong MC, Avanzini S, Mosconi M, et al. Enterostomy-related complications in Hirschsprung's disease in a single cohort. Minerva Pediatr (Torino). 2023 Oct;75(5):711-8. Abstract

101. Sutthatarn P, Lapidus-Krol E, Smith C, et al. Hirschsprung-associated inflammatory bowel disease: a multicenter study from the APSA Hirschsprung disease interest group. J Pediatr Surg. 2023 May;58(5):856-61. Abstract

102. Ahmad H, Levitt MA, Yacob D, et al. Evaluation and management of persistent problems after surgery for Hirschsprung disease in a child. Curr Gastroenterol Rep. 2021 Oct 11;23(11):18. Abstract

103. Ahmad H, Yacob D, Halleran DR, et al. Evaluation and treatment of the post pull-through Hirschsprung patient who is not doing well; update for 2022. Semin Pediatr Surg. 2022 Apr;31(2):151164. Abstract

104. Mei F, Wu M, Zhao L, et al. Probiotics for the prevention of Hirschsprung-associated enterocolitis. Cochrane Database Syst Rev. 2022 Apr 26;4(4):CD013714.Full text  Abstract

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